Villous adenoma of the urinary tract is uncommon. It occurs in the elderly patients with a predilection for the urachus, dome, and trigone of the urinary bladder; rare cases involve the ureters or urethra. We herein report a rare case of recurrent villous adenoma of urinary bladder and ureter. CASE REPORT: 49 yr male patient presented with history of passing mucous perurethrally for the past 4 months, associated with burning micturition, hesitancy, frequency. He underwent trans urethral resection of bladder tumor for two times and had recurrence involving the trigone, dome, left lateral wall, bladder neck, prostatic urethra and right ureteric stump. He underwent radical cystoprostatectomy with ileal conduit. Histopathological examination showed villous adenoma with moderate dysplasia. CONCLUSION: Recurrence of the original tumor or subsequent development of adenocarcinoma is rarely seen. In our case the tumor was highly recurrent with bladder outlet obstruction and was managed by ablative surgery. A through follow up of these patients is recommended.