<p>Schwannomas are benign tumors originating from the neural crests (schwann cells), which are cells that form the nerve sheath of peripheral nerve fibers. Around 25-45% cases of schwannomas occur in the head and neck, of which less than 4% occurs in the nasal cavity and the paranasal sinuses. Isolated schwannomas of the maxillary sinus appear to be extremely rare. We report a case of an isolated maxillary schwannoma in a 45 years old lady who presented with swelling in the right cheek for 1 year and right sided nasal obstruction for 4 months. The swelling was not associated with epistaxis, fever, headache or visual disturbances. We report this case keeping in mind the rarity in occurrence of isolated maxillary schwannomas</p>