Congenital midline cervical cleft with an underlying bronchogenic like cyst

Vure, Srinivas; Pang, Karl H.; Hallam, Lavinia; Lui, Millie; Croaker, David

doi:10.1007/s00383-009-2419-6

Cited by 15 publications

(7 citation statements)

References 13 publications

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“…In their retrospective case series of 8 patients, Achard et al [17] found only one patient with an atrophic kidney. Some authors found that CMCC can be associated with other anomalies like thyroglossal duct cyst [21], bronchogenic cyst [22], or a midline cleft from mandible to sternum [23].…”

Section: Discussionmentioning

confidence: 99%

Congenital Midline Cervical Cleft and W-Plasty: Our Experience

Bahakim

François

Abbeele

2018

International Journal of Otolaryngology

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Objectives Congenital midline cervical cleft (CMCC) is a very uncommon congenital anomaly of the midline anterior neck, and although it has very pathognomonic features (including nipple-like protuberance), it could be mistaken for other congenital neck lesions, such as thyroglossal duct cyst and branchial apparatus anomalies. Thus, it represents a challenging diagnosis. In this 21-patient series, we discuss the clinical features of CMCC, its pathophysiology characteristics, and its modalities management. Material and Methods We conducted a retrospective chart review of children presenting with CMCC at our institution, between January 1998 and January 2016. Results Twenty-one patients were identified with CMCC. Ages ranged between 1 day and 14 years. The length of the lesion varied from 0.5 to 5 cm, and the size of the skin tag varied from 0.2 to 1.5cm. No other significant associated anomalies were found. Surgery was the mainstay treatment, and no recurrence was found. W-plasty was used in most patients to close the defect. Conclusion With a little more than 200 published cases, our series represents the largest series worldwide. The lesion is usually isolated, and no further investigation is required. Surgery is the mainstay of treatment, with complete excision being usually curative. It should be treated at an early age to prevent complications. In our experience, W-plasty was a good alternative to the most commonly used Z-plasty, in skin closure, with respect to both aesthetic and functional results.

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Section: Discussionmentioning

confidence: 99%

Congenital Midline Cervical Cleft and W-Plasty: Our Experience

Bahakim

François

Abbeele

2018

International Journal of Otolaryngology

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“…10 The midline cervical cleft may be a solitary deformity, but there are cases where it is combined with thyroglossal duct cyst, ectopic bronchogenic cyst, branchial cyst, midline hemangioma, ectopia cordis, cleft lip, mandible or tongue, cleft sternum, absence of hyoid bone or thyroid cartilage, or congenital heart disease. 7,11,12 This eventually results in a fourth clinical issue, failure of diagnosis of any of these disorders. 1 Different theories have been proposed on the embryological origin of the CMCC.…”

Section: Discussionmentioning

confidence: 99%

Congenital Midline Cervical Cleft: A Case Report with Review of Literature

Jaiswal¹,

Behera²,

Membally³

et al. 2017

International Journal of Head and Neck Surgery

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Aim: To highlight a rare case of a congenital midline cervical cleft (CMCC) in context with embryological theories/hypothesis, presentation, and management along with review of literature. Introduction: Congenital midline cervical cleft is a rare but interesting anterior neck anomaly with controversial theories/ hypothesis regarding its embryogenesis. Case report: We describe here a classical case of midline cervical cleft that presented at birth with a cephalocaudal orientation, extending from the level below the hyoid bone to the suprasternal notch with a length of 3 cm and width of 0.5 cm. At 6 months of age, the lesion was excised and closure was done by multiple Z-plasty, with satisfactory results. Discussion: Although the diagnosis is clinical, it is frequently misdiagnosed. The associated clinical features could include thyroglossal duct cysts, cleft lip/mandible/sternum, cervical contractures, mandibular spurs, microgenia, and/or bronchogenic cysts. If it is not treated at an early age, it can result in complications like webbing of the neck, dental malocclusion, and restricted neck movements. Conclusion: Earliest recognition of CMCC and proper intervention can provide better esthetic and functional prognosis. Clinical significance: A correct earlier recognition of the lesion and appropriate surgical management are key to avoid longterm complications.

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“…The midline cervical cleft may be a solitary deformity, but there are cases where it is combined with thyroglossal duct cyst, ectopic bronchogenic cyst, branchial cyst, midline hemangioma, ectopia cordis, cleft lip, mandible or tongue, cleft sternum, absence of hyoid bone or thyroid cartilage, or congenital heart disease [9, 12, 16]. This eventually results to a fourth clinical issue, failure of diagnosis of any of these disorders [1].…”

Section: Discussionmentioning

confidence: 99%

Congenital Midline Cervical Cleft: Diagnosis, Pathologic Findings, and Early Stage Treatment

Sinopidis

Kourea

Panagidis

et al. 2012

Case Reports in Pediatrics

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Congenital midline cervical cleft is a very uncommon malformation of the anterior neck, with less than 100 cases reported in medical literature. Herein we present a case of a female neonate with this anomaly. A detailed description of the macroscopic and microscopic characteristics is performed. As it is derived from the natural history of the lesion, prompt clinical diagnosis, and operative treatment during early infancy predispose to a better aesthetic and functional prognosis.

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Congenital midline cervical cleft with an underlying bronchogenic like cyst

Cited by 15 publications

References 13 publications

Congenital Midline Cervical Cleft and W-Plasty: Our Experience

Congenital Midline Cervical Cleft and W-Plasty: Our Experience

Congenital Midline Cervical Cleft: A Case Report with Review of Literature

Congenital Midline Cervical Cleft: Diagnosis, Pathologic Findings, and Early Stage Treatment

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