Cystic lymphangioma of breast and axillary region in an adult: a rare presentation

Shukla, Samir; Shivhare, Rahul; Lal, Vikas; Rathore, Deepak

doi:10.18203/2349-2902.isj20205911

Cited by 3 publications

(4 citation statements)

References 16 publications

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“…Adult mammary CH cases are exceedingly rare. 4 , 5 Few cases have been reported in the last 50 years worldwide, majority reported cases were female. Park et al 4 2018 reported the first simultaneous breast and axillary CH case.…”

Section: Discussionmentioning

confidence: 99%

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Rare Cystic Hygroma of the Axilla and Breast in Adults, Case Report, Long-Term Follow-Up and Literature Review: An Experience from Saudi Arabia

Al-Ameer

Alahmar²,

Shawafgfeh³

et al. 2023

IMCRJ

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Cystic hygroma (CH) in adults is a rare condition. Most CH cases are diagnosed at birth or during the first two years of life. Head and neck are the most common sites. There is scanty information about the natural history and follow-up of adult patients with axillary and breast CH. Hence, we present this case to shed some light on the natural history, complications, and a new suggested modality of treatment to deal with the complications. Case Presentation: We report a case of a 39-year-old female who presented after ten years of excision of the right axillary CH with massive breast edema and recurrence of cysts in the ipsilateral breast and axilla. The insertion treated the edema of a breast-peritoneal shunt. Discussion: The procedure was performed by inserting a normal V-P shunt catheter without a reservoir through a small incision in the inframammary fold toward the breast and another tiny incision at 10 of the clock in the right breast for fixation in the breast parenchyma. A catheter was inserted through a small incision on the right lumbar spine without intraperitoneal fixation after the catheter was inserted subcutaneously. Conclusion: This case report shows that adult CH can reoccur. To our knowledge, this is the second case of CH concomitantly involving the breast and axilla. The shunt of the edematous fluid to the peritoneal cavity can give hope for intractable breast edema treatment.

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Section: Discussionmentioning

confidence: 99%

“…The cause of CH is generally unknown, but there is evidence of causes, 5 such as viral infections, trauma, and congenital misrouting between lymphatic and venous pathways. Chromosomal abnormalities have been identified at CH, commonly involving Noonan syndrome, trisomies 13, 18, and 21, and Turner syndrome.…”

Section: Introductionmentioning

confidence: 99%

Rare Cystic Hygroma of the Axilla and Breast in Adults, Case Report, Long-Term Follow-Up and Literature Review: An Experience from Saudi Arabia

Al-Ameer

Alahmar²,

Shawafgfeh³

et al. 2023

IMCRJ

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“…CH is rare in adult and very few cases have been reported in literature [4,5,7,[10][11][12][13][14][15][16][17][18][19][20][21]. Development of CH in adulthood is caused by delayed proliferation of cell rests with infection, trauma, or iatrogenic stimuli as being the predisposing factors.…”

Section: Discussionmentioning

confidence: 99%

“…Its occurrence in axilla is extremely rare [4][5][6][7]. At the Indian subcontinent, only three case reports are available in the literature [8][9][10][11]. To the best of our knowledge, this is the first reported case of unilocular CH in the axillary region in an adult male from India.…”

Section: Introductionmentioning

confidence: 99%

Adult-Onset Cystic Hygroma in Axilla: A Rare Case Report From India and Literature Review

Pandey¹,

Kumar²,

Maheshwari³

et al. 2021

IJMMR

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Background. Cystic hygroma (CH), occurs in 1/6000 live births and in 90% of cases develops in age less than 2 years old. They are mainly located in cervicofacial region. Adult-onset CH is very rare. Objective. The aim of this study is to review literature to discuss the clinical presentation, diagnosis, and treatment of CH in adults through a case report of unilocular CH in the axillary region in an adult male from India. Methods. A first case report of unilocular CH in axillary region in an adult male from India is being investigated. Results. Here we report a case of unilocular CH in the axillary region in a 49-year-old male with a 14x16x8 cm cystic swelling in left axilla with a history of aspiration failure. Contrast-enhanced MRI (CEMRI) showed well-defined thin walled, unilocular cystic lesion which appeared hyperintense on T2 & STIR and hypointense on T1W1 and showed thin peripheral rim of enhancement on post contrast images. The patient underwent surgical excision and the diagnosis of a pathological CH was established. His postoperative recovery was uneventful and had no evidence of recurrence. Conclusion. Due to rarity of adult-onset unilocular CH in axilla, its evaluation for prompt diagnosis and definitive treatment to prevent recurrence and complications is urgent. Furthermore, this is the first reported case from India which has been successfully managed at a peripheral hospital in Northeast-India and our report of this case contributes to the evidences supporting the role of CH in a differential diagnosis for masses in the adult axilla, especially in acute phase with no predisposing factors.

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Acquired cystic lymphangioma imitating breast cancer recurrence

Choayb

Jidal

Zahi

et al. 2023

Radiology Case Reports

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Cystic lymphangioma of breast and axillary region in an adult: a rare presentation

Cited by 3 publications

References 16 publications

Rare Cystic Hygroma of the Axilla and Breast in Adults, Case Report, Long-Term Follow-Up and Literature Review: An Experience from Saudi Arabia

Rare Cystic Hygroma of the Axilla and Breast in Adults, Case Report, Long-Term Follow-Up and Literature Review: An Experience from Saudi Arabia

Adult-Onset Cystic Hygroma in Axilla: A Rare Case Report From India and Literature Review

Acquired cystic lymphangioma imitating breast cancer recurrence

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