Fibromuscular dysplasia (FMD) is an idiopathic, segmental, non-inflammatory and non-atherosclerotic disease
that affects arterial walls, leading to stenosis of small and medium-sized arteries. FMD mostly involves renal and intracranial
arteries and only in few patients is associated with macroaneurysms (RAAs). We present the case of a 45-years old
woman with recent history of grade 2 hypertension that suffered of subarachnoid haemorrhage due to rupture of a basilar
artery aneurysm. The cerebral aneurysm was immediately treated by coil embolization and an abdominal angio-CT scan
was performed to investigate the presence of renovascular hypertension. The exam showed the presence of FMD of the
renal arteries associated with presence of bilateral RAAs. Due to the high risk of rupture, the bigger aneurysm (2,5 cm diameter)
present on the left artery was immediately treated by coil embolization. The fusiform aneurysm, present on the
right renal artery, was instead treated one year later by using two flow diverter stents. After three years, an angiographic
study showed that both cerebral and renal aneurysms were excluded from the blood flow without evidence of arterial
restenosis.