Infantile cortical hyperostosis of the mandible

Infantile cortical hyperostosis, masquerading as osteomyelitis: a case report with three year follow up and review of the literature

“…Mandible is most commonly involved site followed by clavicle, ulna and other long bones. 2,3 Isolated cases of entrapment neuropathy causing Erbs palsy and facial palsy have been reported in literature.…”

“…1 It is an episode of massive supperiostel newbone formation involving mandible, clavicle and diaphysis of long bones. 2,3 It is characterized by bone pain, irritability, fever, psedoparalysis of affected limbs and soft tissue swelling. The presentation is variable and can mimic that of osteomyelitis but involvement of mandible is characteristic of Caffeys disease.…”

A localised soft tissue and bone enlargement in an infant mandible

“…There is no predilection for sex, race or social status and the exact aetiology of this condition is still unknown. However, some of the proposed causes are infections, immunological defects, primary arterial abnormalities and genetic abnormalities 7. Its characteristic triad of manifestation of soft tissue swelling, underlying cortical bone thickening and irritability in behaviour, was seen in our case.…”

“…Accordingly no treatment was administered in our case. But the inflammatory nature of ICH has led to treatment trials with anti-inflammatory agents such as steroids like prednisolone and non-steroidal anti-inflammatory drugs such as indomethacin, which have been reported to provide symptomatic relief to some patients 7. Despite its inherent self-limiting nature, recurring forms of this disease may occur and persist for many years.…”