Background: Intramuscular hemangioma is a kind of benign vascular tumors often occurs in the lower extremity, which occurs in the gluteus medius muscle, and was misdiagnosed as lumbar disc herniation is rarely reported.Case presentation: A 36-year-old female who complaint of accidental pain of the left buttock. She was diagnosed as lumbar disc herniation, and accept the treatment. The symptom slightly relieved, but will relapse soon. Until she takes the X-ray and MRI, a mass was found in the gluteus medius muscle, which was suspected of malignant tumor. Then the tumor was resected and the final diagnosis is intramuscular hemangioma. The symptoms disappear completely and not recurrent.Conclusion: There are usually no special symptoms in patients with intramuscular hemangioma, so it is often misdiagnosed, when the treatment effect is not satisfied, the cause should be timely and correctly analyzed.