Massive pneumatic expansion of lymphatic vessel resulting in cystic lesions in the pulmonary parenchyma: A rare case of persistent interstitial pulmonary emphysema in a non-ventilated infant

Fujishiro, Jun; Komuro, Hiroaki; Ono, Kentaro; Urita, Yasuhisa; Shinkai, Toko; Minami, Yuko; Kawabata, Yoshinori; Kishimoto, Hiroshi; Masumoto, Kouji

doi:10.1016/j.jpedsurg.2012.09.035

Cited by 2 publications

(1 citation statement)

References 17 publications

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“…However, these diseases also have pathologic differences. In PIE, the giant cell reaction that forms a partial lining of the air spaces is a characteristic microscopic feature, indicating a reaction to the interstitial air (16, 17, 18). This finding was absent in our case.…”

Section: Discussionmentioning

confidence: 99%

Pneumonectomy Case in a Newborn with Congenital Pulmonary Lymphangiectasia

et al. 2014

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Congenital pulmonary lymphangiectasia (CPL) is a rare lymphatic pulmonary abnormality. CPL with respiratory distress has a poor prognosis, and is frequently fatal in neonates. We report a case of pneumonectomy for CPL in a newborn. An infant girl, born at 39 weeks' after an uncomplicated pregnancy, exhibited respiratory distress 1 hr after birth, which necessitated intubation and aggressive ventilator care. Right pneumonectomy was performed after her symptoms worsened. Histologic examination indicated CPL. She is currently 12 months old and developing normally. Pneumonectomy can be considered for treating respiratory symptoms for improving chances of survival in cases with unilateral CPL.Graphical Abstract

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Section: Discussionmentioning

confidence: 99%

Pneumonectomy Case in a Newborn with Congenital Pulmonary Lymphangiectasia

et al. 2014

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A Case of Pulmonary Interstitial Emphysema and Systematic Review of Literature in Management Approach

La Regina,

Arena,

Riccardi

et al. 2023

CRMR

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Background: Pulmonary interstitial emphysema (PIE) is a rare pathology characterized by the abnormal and harmful presence of air in the interstitial tissues of the lung. This condition is often related to barotrauma caused by mechanical ventilation, but it can be exceptionally seen in healthy infants. The main causes of PIE are respiratory distress syndrome (RDS), mechanical ventilation or positive pressure ventilation, prematurity, meconium aspiration syndrome, pulmonary infection, amniotic fluid aspiration, and incorrect endotracheal tube placement. To date, there is no standard treatment for PIE, based on the clinical and localization of PIE conservative and non-conservative therapies are described. Methods: We describe a case of a very premature infant with severe respiratory failure secondary to RDS and unilateral left sided PIE with lung herniation treated with conservative therapy like selective intubation, steroid therapy, lateral position, and lastly, oxygen supplementation without ventilatory assistance. Furthermore, we have carried out a systematic literature review for the past 15 years (2007-2022). A systematic review, using an evidence-based algorithmic approach, was conducted following the Preferred Reporting Items for Systematic Reviews and Meta-Analyses (PRISMA) guidelines. Results: Our search, after the selection, produced a total of 24 articles, which were revised. Conclusion: In our case oxygen supplementation without ventilatory assistance resulted in successful resolution of the left PIE. Discontinuation of ventilatory care played a crucial role. Considering the management reported in literature, our aim is to perform a systematic literature review by adding our experience to the available knowledge on therapy for unilateral PIE.

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Massive pneumatic expansion of lymphatic vessel resulting in cystic lesions in the pulmonary parenchyma: A rare case of persistent interstitial pulmonary emphysema in a non-ventilated infant

Cited by 2 publications

References 17 publications

Pneumonectomy Case in a Newborn with Congenital Pulmonary Lymphangiectasia

Pneumonectomy Case in a Newborn with Congenital Pulmonary Lymphangiectasia

A Case of Pulmonary Interstitial Emphysema and Systematic Review of Literature in Management Approach

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