Background:Pneumosinus dilatans (PSD) is a rare pathological paranasal sinus expansion.
This condition is usually symptomatic or cosmetically apparent, requiring
surgical intervention. Multiple hypotheses have been postulated as to the
cause of this condition; however, the precise cause and pathogenesis remain
obscure.Case report and Methods:An 11-year-old boy presented with right eye bulging and was subsequently
found to have PSD of the maxillary sinus. A search was conducted of the
PubMed electronic database, using the keywords “pneumosinus dilatans,”
“pneum(oco)ele,” “pneum(oc)ele,” “pneum(atoco)ele,” and “air cyst.” Articles
published in English were reviewed.Results:The literature review identified 29 cases of PSD involving the maxillary
sinus. The mean age of presentation was 25 years old. Only the right
maxillary sinus was affected in 16 cases, followed by the bilateral sinuses
in 7 cases and the left sinus in 6 cases. In 5 cases, all paranasal sinuses,
along with the maxillary sinus, were expanded. The most common presenting
symptom was facial swelling, which was found in 55% of the cases, followed
by proptosis and pain. Computed tomography is the gold standard radiological
method for diagnosing PSD.Conclusions:Pneumosinus dilatans is a rare condition that is usually symptomatic and
requires surgical intervention. The etiology of the disease is attributed to
multiple hypotheses, but more studies are needed to explore this condition
further.