A 28-year-old male patient applied to our clinic for the complaint of an enlarged mass with occasional discharge behind the left ear. Physical examination revealed a total of three fistula ostiums, the largest of which was large base, mobile, soft consistency, painless, and approximately 2x1 cm in size in the left postauricular region. Histopathological examination of the total excision mass was reported as pilonidal sinus. In this article, a rare case of pilonidal sinus in the postauricular region is presented in the light of clinical findings, diagnosis, surgical treatment and current literature.