Recurrent right sublingual ranula, concomitant with ipsilateral submandibular salivary gland aplasia

Albsoul, Nader; Obeidat, Firas; Al-Taher, Raed; Jubouri, Shams; Hadidy, Azmy M.

doi:10.1016/j.ijscr.2012.10.021

Cited by 11 publications

(13 citation statements)

References 22 publications

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“…1,5,9 There seems to be a higher frequency among young adults in their second and third decades as well as in children younger than 10 years, with a slight female preponderance. 7,[10][11][12] Sublingual ranulas form above the mylohyoid muscle, within the sublingual space, and are most commonly observed as a bluish cystic lesion below the tongue. When the fluid pressure of the mucocele ruptures and dissects through the mylohyoid muscle into the submandibular or submental space, it is termed a plunging or diving ranula.…”

Section: Discussionmentioning

confidence: 99%

“…When the fluid pressure of the mucocele ruptures and dissects through the mylohyoid muscle into the submandibular or submental space, it is termed a plunging or diving ranula. [1][2][3][4][5][6]9,[11][12] These extravasation cysts tend to extend into the submandibular triangle but have been observed to extend superiorly into the parapharyngeal space as far as the skull base, inferiorly into the supraclavicular area and upper mediastinum, or posteriorly into the retropharyngeal space. 2,7,12 Some physiologic mechanisms that contribute to plunging ranulas have been proposed [5][6][7]13 : Plunging ranulas are usually seen in conjunction with a sublingual ranula and rarely form independent of the oral component.…”

Section: Discussionmentioning

confidence: 99%

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Plunging Ranula: A Case Report

Ayers

2018

Journal of Diagnostic Medical Sonography

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Recognized over 1000 years ago during the Byzantine era, the term ranula is derived from the word rana, which is Latin for frog, as the swollen appearance of the sublingual mucous membranes resembles the translucent underbelly of a frog. 1-7 There are two types of ranulas: simple and plunging. Sublingual ranulas form underneath the mucous membranes of the floor of the mouth above the mylohyoid, whereas plunging ranulas "plunge" by extending below the mylohyoid into the submandibular or parapharyngeal space, presenting as neck masses. 2-3 Multiple surgical techniques have been used, ranging from marsupialization, incision and drainage, excision of the ranula only, excision of the sublingual gland along with ranula, and sclerotherapy. Recurrence rates vary depending on type of procedure performed. It has been noted that because these extravasation cysts originate from the sublingual salivary gland, excision of the sublingual gland along with ranula is the most effective treatment. 1,5,6 Case Report A 25-year-old female patient presented with a 4-month history of a unilateral, nontender, enlarging, soft submental mass, extending to her right submandibular region. There was no history of trauma, infection, or any oral or neck surgical procedures. Physical examination demonstrated a diffuse, oval, soft tissue prominence with normal overlying skin extending from the right mandible to the submental region. A sonogram was ordered to further characterize the mass (see Figures 1 and 2). The patient's area of diffuse swelling was scanned using a submental approach with a high-frequency ML6-15 linear-array transducer (GE Logiq 9; GE Healthcare, Waukesha, WI). Sonographic findings included a large cystic mass with two components. The more superficial component measured 3.6 × 1.3 × 2.9 cm. The deeper component measured 3.7 × 2.9 × 1.3 cm and extended along the medial aspect of the mandible. Communication between the two components was identified during sonography. A portion of the sac plunged through the muscle 767632J DMXXX10.

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Section: Discussionmentioning

confidence: 99%

Section: Discussionmentioning

confidence: 99%

Plunging Ranula: A Case Report

Ayers

2018

Journal of Diagnostic Medical Sonography

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“…Salivary gland aplasia is a rare condition with only a small number of cases reported worldwide . The aetiology of major salivary gland aplasia is unknown.…”

Section: Discussionmentioning

confidence: 99%

“…Salivary gland aplasia is a rare condition and its precise incidence is unknown . To date, only about 50 cases of major salivary gland agenesis have been reported in the literature, describing both partial and complete agenesis …”

Section: Introductionmentioning

confidence: 99%

Hyposalivation in a 16‐year‐old girl: a case of salivary gland aplasia

Frydrych

Koong

2014

Australian Dental Journal

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Salivary gland aplasia is a rare condition with only a small number of cases reported worldwide. It is more commonly seen in males and can occur either in isolation or association with other defects or syndromes. It may or may not occur with a hereditary background. Scant literature exists detailing the status of sublingual salivary glands in patients with any form of major salivary gland aplasia. This case report describes the clinical and magnetic resonance imaging presentation of a 16-year-old girl with major salivary gland aplasia detailing the status of all six major salivary glands.Keywords: Hyposalivation, salivary gland aplasia.Abbreviations and acronyms: CPP-ACP = casein phosphopeptide-amorphous calcium phosphate; LADD = lacrimo-auriculo-dentodigital; MRI = magnetic resonance imaging.

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“…Congenital ranulas are rare, with an incidence of 0.74%, with prenatal diagnosis rarely reported [4] . Whilst ranulas can infrequently recur [5] , contralateral occurrence of congenital ranulas has not yet been described in the literature.…”

Section: Introductionmentioning

confidence: 99%

Serious neonatal airway obstruction with massive congenital sublingual ranula and contralateral occurrence

George

Mirza

Solanki

et al. 2015

Annals of Medicine &Amp; Surgery

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BackgroundCongenital ranulas seldom occur, with bilateral presentation and prenatal diagnosis reported very rarely. We believe this is the first reported case of a neonate with a antenally diagnosed massive congenital ranula, who went on to develop a non-contiguous contralateral ranula, both contributing to obstruction in a complex paediatric airway.Case reportA female neonate was born to a non-primagravid mother via a planned elective caesarean section due to a lower facial defect and oral cyst. Antenatal aspiration of the pseudocyst was performed under ultrasound guidance with limited success. In the immediate post-natal period a poor airway was observed and the cyst was subsequently marsupialised. With the development of macroglossia secondary to oedema and tongue base collapse the airway was secured through surgical tracheostomy. A subsequent ultrasound scan revealed the presence of a second solitary cystic mass on the contralateral side. After careful excision of the contralateral pseudocyst, tongue function improved, with the resolution of a safe airway which permitted successful decannulation. A planned definitive procedure antenatally did not result in the anticipated improvement in function. However the subsequent development of a second non-contiguous pseudocyst and further surgical management resulted in a safe airway, improved masticator function and the ability to thrive.ConclusionsThe prenatal diagnosis of congenital ranulas have been seldom reported, with no reported cases of contralateral occurrence and airway obstruction from an intraoral ranula. This rare case highlights the need for a well considered contingency plan when surgery is required for a neonatal airway at risk.

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Recurrent right sublingual ranula, concomitant with ipsilateral submandibular salivary gland aplasia

Abstract: Further research may prove similar associations between oral ranula and salivary gland aplasia, which may have clinical implications on diagnostic and management plan decisions.

Cited by 11 publications

References 22 publications

Plunging Ranula: A Case Report

Plunging Ranula: A Case Report

Hyposalivation in a 16‐year‐old girl: a case of salivary gland aplasia

Serious neonatal airway obstruction with massive congenital sublingual ranula and contralateral occurrence

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