Tongue harmatoma in association with cleft palate: Case report

Cosmas, Uwakwe; Onah, Ifeanyi Igwilo

doi:10.4103/jclpca.jclpca_34_17

Cited by 2 publications

(7 citation statements)

References 5 publications

Supporting

Mentioning

Contrasting

Order By: Relevance

“…40 However, fat cells were also reported to be predominant in 1 patient. 30 Similarly, the histological findings of our patient revealed fatty areas and muscle mass. Lingual hamartomas are rare congenital lesions, mostly asymptomatic, and therefore the true prevalence is unknown.…”

Section: Discussionsupporting

confidence: 74%

“…The cases were reported from various geographical regions, including 3 cases from Japan 21,23,27 and the USA, 22,24,29 2 cases from India, 19 China, 31,32 and Germany, 25 and 1 case from Canada, 26 South Africa, 28 Croatia, 20 and Nigeria. 30 Except for one article written in Chinese, 32 all other case reports were in English.…”

Section: Resultsmentioning

confidence: 99%

“…Among the various studies, MRI 25,28,32 and CT 26,27,32 scans were used to diagnose the pathology. In addition, the Tc-99 scan 19 and ultrasonography (USG) neck 29,30 were used to rule out lingual thyroid. On the other hand, few studies employed ECG 21,32 and USG of kidney and heart.…”

Section: Resultsmentioning

confidence: 99%

“…However, if the hamartoma is associated with a cleft palate, it appears reasonable to excise the mass before the cleft palate repair to avoid interferences of tongue mass with the repair. 30 Furthermore, the inflammation of the tongue following hamartoma excision might cause respiratory distress. Hence, the cleft palate repair may be postponed for at least 8 to 12 weeks to reduce the chances of dyspnea.…”

Section: Discussionmentioning

confidence: 99%

“…Six articles were further excluded as they were not cases of lingual hamartoma or associated with cleft palate and hence did not meet the selection criteria. Lastly, 14 articles [19][20][21][22][23][24][25][26][27][28][29][30][31][32] were considered after a full-text review (Figure 4).…”

Section: Systematic Reviewmentioning

confidence: 99%

See 4 more Smart Citations

A Rare Case of Cleft Palate Associated With Tongue Hamartoma: A Case Report and Systematic Review

Dash

Chauhan

Sennimalai

et al. 2022

The Cleft Palate Craniofacial Journal

View full text Add to dashboard Cite

Introduction Palate development involves a genetic regulation through a complex molecular mechanism that may be disrupted by environmental factors, resulting in impaired fusion and cleft palate formation. An encounter with a case of cleft palate due to dorsal tongue hamartoma prompted us to perform this systematic review. Objective To review the clinical profile and management approach for a case with cleft palate and tongue hamartoma. Design A systematic literature search was conducted using keywords related to cleft palate and tongue hamartoma in PubMed, Scopus, MEDLINE, and Scielo databases through December 2021, with no time or language restrictions. Patients, Participants Studies reporting patients with cleft palate and tongue hamartoma were included. Main outcome measure(s) Information related to clinical profile, diagnostic tests, histopathology, management, and outcomes were extracted. Fourteen relevant publications were identified with 16 cases reported so far. Among them, thirteen patients were females (81.25%), and 3 were males (18.75%). The age of presentation varied from birth to 19 years. Oral-facial-digital syndrome (type II) was the most commonly associated syndrome. Congenital tongue hamartoma with cleft palate is a rare presentation, which can present as an isolated entity or part of a syndrome. Genetic evaluation is warranted, particularly for multiple hamartomatous lesions. The preferred treatment is immediate excision of hamartoma while following a standard timeline for palatoplasty.

show abstract

Section: Discussionsupporting

confidence: 74%