AbstractsWilms tumor (WT) is the most common malignant, solid renal tumor in children. Most recurrent or metastatic WT occur within the first 2 years after the primary diagnosis. Urethral metastases in WT are very unusual and to the best of our knowledge have been reported only twice within the English literature. Those two cases had a poor outcome suggesting that urethral metastasis in recurrent WT is an indicator of poor prognosis. We report a third case of urethral recurrence of WT and reviewed the two previously reported cases in details.