Diffuse hemolymphangioma of the rectum: A report of a rare case

Intraabdominal lymphangioma is rare and comprises 5% of all lymphangiomas. In adults, it is less common than in children, and because of a benign progress lymphangioma is usually asymptomatic and its diagnosis is quite difficult. However, it is recommended to extirpate lymphangioma surgically to avoid complications. There is the question if lymphangioma should be completely excised to avoid relapses. We present a case of cavernous lymphangioma in an adult male who underwent a partial resection of the tumour. After ten years of observation, there is no evidence of tumour recurrence. Key words: lymphangioma, cavernous, cysticPilvinės limfangiomos pasireiškia retai ir sudaro mažiau nei 5 % visų limfangiomų. Suaugusiesiems limfangiomos pasitaiko rečiau nei vaikams, dėl gerybinės eigos jos būna besimptomės ir sunkiai diagnozuojamos. Vis dėlto siekiant išvengti komplikacijų rekomenduojamas chirurginis limfangiomų šalinimas. Literatūroje išlieka diskusinis klausimas, ar būtina visiškai pašalinti limfangiomas siekiant išvengti jų atkryčio. Mes aprašome kaverninės limfangiomos atvejį vyrui, kuriam buvo atlikta dalinė rezekcija. Po dešimties stebėjimo metų atkryčio nerasta.

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“…In cases of acute bleeding, angiography and embolization can be applied [16]. However, in our experience, only one patient had anemia.…”

Section: Discussionmentioning

confidence: 80%

Abdominal lymphangiomas in adults: case report and literature review

Šileikis

Danys

Žaldokas

et al. 2015

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“…Most of the intestinal HLs are incidental findings, during an endoscopy or a radiological study [3–6]. …”

Section: Discussionmentioning

confidence: 99%

“…Angiography and embolization may be used in acute bleeding cases, but there is a risk of new bleeding [3]. …”

Section: Discussionmentioning

confidence: 99%

Duodenal hemangiolymphangioma presenting as chronic anemia: a case report

et al. 2016

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BackgroundLymphangiomas are a heterogeneous group of congenital vascular malformations characterized by cystic dilation of lymphatic vessels. They can occur at any age, but they are more common during childhood and in cutaneous localizations. Hemangiomas and vascular malformations of the gastrointestinal tract are very uncommon. Most are asymptomatic and diagnosis is often made as an incidental finding during endoscopy. On rare occasions the initial manifestation can be chronic anemia due to low grade gastrointestinal bleeding. They constitute an unusual manifestation and there is a low incidence of this type of tumor.Case presentationWe report the case of a 43 year-old latin female, with a 2-year history of chronic anemia requiring blood transfusion. Hemoglobin and Hematocrit count were low, therefore further studies were required to rule out bleeding sources or other causes of anemia. Enteroscopy findings showed a 35 mm lesion taking up 50 % of the circumference in the distal duodenum, with raised whitish edges secondary to confluent lymphangiectasia, a center with a vascular appearance and active bleeding spots. Biopsy samples dyed with India ink confirmed the diagnosis of hemangiolymphangioma.ConclusionDiagnostic difficulties in this case, highlight the need to include hemangiolymphangioma in the differential diagnosis of chronic anemia as well as the need for multiple diagnostic methods to confirm the presence of the condition.

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“…Hemolymphangioma has been previously detected at the pancreas (5,7-12), spleen (13)(14)(15)(16), stomach (1,17), rectum (18), mediastinum (19)(20)(21), chest wall (22)(23)(24)(25), small intestine (26), extremities (3,27,28), cervix (29,30), pericardium (31), oral region (32), esophagus (33), axilla (34), retroperitoneal space (35,36), adrenal gland (37), abdomen (38), duodenum (4) and hepatica (39), as well as on the tongue (40,41) and orbit (42,43). However, to the best of our knowledge, no studies have reported this type of tumor in the waist region, as determined by a review of the medical literature until June 2014 using the PubMed database (http://www.ncbi.nlm.nih.gov/pubmed; accessed on 9th June 2014).…”

Section: Introductionmentioning

confidence: 99%

“…In cases of tumor recurrence, conservative treatment methods such as laser therapy, may be applied (3,44). Generally, the prognosis of hemolymphangioma is good (3,4,13,17,18), however, careful follow-up is required.The present study reported the case of a 17-year-old male patient with hemolymphangioma on the waist and reviewed the characteristics of this disease based on the existing literature. …”

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confidence: 99%

Hemolymphangioma of the waist: A case report and review of the literature

Pang

Yang

et al. 2015

Oncology Letters

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Abstract. Hemolymphangioma is a malformation of the lymphatic and blood vessels. To the best of our knowledge, only a limited number of hemolymphangioma cases have been reported in the literature thus far, with no cases developed in the waist region. The present study reported the case of a 17-year-old male patient with hemolymphangioma growing on the waist, presented with back pain for four months. Upon physical examination, the lesion was identified to be oval in shape, soft and compressible, with mild tenderness. No abnormalities were detected in the results of laboratory examinations. However, a magnetic resonance imaging (MRI) scan revealed a tumor with low signal intensity on T1-weighted imaging (WI) and high signal intensity on T2-WI. The mass was successfully removed during surgery. During the seven-month follow-up period, the patient was asymptomatic with no evidence of recurrence. The present study discussed the imaging findings and pathological features of this uncommon case and reviewed the relevant literature. IntroductionLymphangioma, also known as angioma lymphaticum, is a congenital malformation of the vascular system, comprising newly-formed lymph spaces and channels (1). Landing and Farber (2) classified this benign malformation in four categories, including capillary, cavernous and cystic (hygroma) lymphangioma, and hemolymphangioma, which is a combination of hemangioma and lymphangioma.Hemolymphangioma is a congenital malformation that may be asymptomatic for a long period of time (3). This lesion is typically considered to be a benign and noninvasive disorder, characterized by the presence of dilated lymphatic spaces, extravasation of red blood cells, hemosiderin deposition and fibrosis (4). Hemolymphangioma formation may be due to venolymphatic communication obstruction between the dysembrioplastic vascular tissue and systemic circulation (5).The incidence of hemolymphangioma is 1.2-2.8 per 1,000 newborn infants (6). Hemolymphangioma has been previously detected at the pancreas (5,7-12), spleen (13-16), stomach (1,17), rectum (18), mediastinum (19-21), chest wall (22-25), small intestine (26), extremities (3,27,28), cervix (29,30), pericardium (31), oral region (32), esophagus (33), axilla (34), retroperitoneal space (35,36), adrenal gland (37), abdomen (38), duodenum (4) and hepatica (39), as well as on the tongue (40,41) and orbit (42,43). However, to the best of our knowledge, no studies have reported this type of tumor in the waist region, as determined by a review of the medical literature until June 2014 using the PubMed database (http://www.ncbi.nlm.nih.gov/pubmed; accessed on 9th June 2014). Complete excision is considered the optimal treatment for hemolymphangioma, which exhibits a low recurrence rate. Non-surgical treatments are also used, including aspiration and drainage, cryotherapy, injection of sclerotic agents, laser therapy and radiotherapy, however, to date, the outcomes of such treatments have been unsatisfactory (3,22). In cases of tumor recurrence, conservative treatmen...

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Diffuse hemolymphangioma of the rectum: A report of a rare case

Cited by 24 publications

References 7 publications

Abdominal lymphangiomas in adults: case report and literature review

Abdominal lymphangiomas in adults: case report and literature review

Duodenal hemangiolymphangioma presenting as chronic anemia: a case report

Hemolymphangioma of the waist: A case report and review of the literature

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