Infant Odontogenic Myxoma: A specific entity

Kadlub, Natacha; Mbou, Valère Belle; Leboulanger, Nicolas; Lepointe, Hubert Ducou; Ansari, Edward; L’Hermine, Aurore Coulomb; Davrou, Julien; Vazquez, Marie‐Paule; Picard, A.

doi:10.1016/j.jcms.2013.07.019

Cited by 19 publications

(29 citation statements)

References 17 publications

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“…They usually present as a slow, painless bony expansion and radiographically, the lesion frequently appears as a unit or multilocular radiolucency with well-defined margins [1]. To our knowledge, 21 cases have been described in infants in the international literature [2]. All these patients, as well as our case, share a characteristic clinical and radiological presentation.…”

Section: Discussionmentioning

confidence: 53%

“…Cranial fasciitis can also have a prominent myxoid background, but this is a extraosseous lesion and express smooth muscle actin. Three cases described in the literature were initially misdiagnosed histopathology as nodular fasciitis [2,5,6].…”

Section: Discussionmentioning

confidence: 99%

“…Recurrence rates average about 25% and usually occur during the first 2 years after excision [1]. However, the literature review of infant odontogenic myxomas shows a low rate of recurrences after conservative surgery (4.76%) [2]. the proliferation index in the MIB-1 reaction was 5%.…”

Section: Introductionmentioning

confidence: 98%

“…Two thirds occur in the mandible and one third in the maxilla, usually associated with a tooth germ. This tumour is uncommon in the paediatric population and exceptional in infants (under 2 years) with only 21 cases described in the literature [2].…”

Section: Introductionmentioning

confidence: 98%

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Infant Odontogenic Myxoma: Case Report and Literature Review of a Specific Entity Recently Described

Bravo-Burguillos¹,

Kreilinger²,

Muñoz³

et al. 2016

Arch Otolaryngol Rhinold

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Odontogenic myxomas are benign mesenchymal neoplasm most of them diagnosed in adults. They are uncommon in the paediatric population and exceptional in infants, with only 21 cases reported in the literature under the age of 2 years. We present a new case of infant odontogenic myxoma, that share the same clinical and radiological presentation with the cases described in the literature. They all presented with a painless paranasal swelling of short-term evolution, usually a few weeks duration (while in children or adults tumours usually develop slowly) and a well-defined, intraosseous, expansible lytic tumour of 3 cm average size in CT-scan examination. Most cases underwent enucleation and curettage with a very low rate of recurrences (4.76%). The aim of this article is to report a new case of this exceptional tumour, whose diagnosis was established at histologic examination. We focus on the importance to undergo a conservative approach in this infant population to minimize the surgical morbidity.These tumours do not metastasize and although malignant transformation to myxosarcoma has been reported is a rare event [3]. Case ReportA healthy 21-month-old male, with no relevant personal or family medical history, presented to our hospital with a persistent swelling on the right side of his face after a minor trauma a few weeks before. The patient had persistent swelling that had no regressed. On physical examination there was an indurated, fixed 4cm mass in his right nasolabial groove, adjacent to the right anterior maxillary wall. The lesion did not enlarge with crying. The overlying skin was normal. Eye position and extra ocular motion were normal. An intraoral examination showed obliteration of the maxillary vestibule. Clinically the lesion looked like a mucocele.In CT-scan examination there was a low-density lesion arising within the anterior medial aspect of the left maxillary bone with erosion of the maxillary sinus and the lateral nasal wall (Figure 1). There was separation of the mass from the nasal-lacrimal duct. Taking into account the history of trauma to the area, the CT scan concluded that the lesion was compatible with post-traumatic cyst.Enucleation of the tumour was performed with curettage of the surrounding bone through a vestibular incision. The patient recovered uneventfully from surgery.On gross pathology, the largest dimension of the lesion was 4cm and it was gelatinous with pale brown colour. Histology revealed a myxoid tumour with haphazardly arranged stellate to spindle-shaped cells in a mucoid-rich intercellular matrix (Figure 2). The cells had an eosinophilic cytoplasm, small round hyperchromatic nuclei and fine chromatin. There was not cellular pleomorphism or nuclear atypia. Immunohistochemical staining was positive for vimentin and

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Section: Discussionmentioning

confidence: 53%

Section: Discussionmentioning

confidence: 99%

Section: Introductionmentioning

confidence: 98%

Section: Introductionmentioning

confidence: 98%

See 2 more Smart Citations

Infant Odontogenic Myxoma: Case Report and Literature Review of a Specific Entity Recently Described

Bravo-Burguillos¹,

Kreilinger²,

Muñoz³

et al. 2016

Arch Otolaryngol Rhinold

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show abstract

“…[12][13][14][15] Recently, one report demonstrated four cases of OM occurring in infants less than 2 years old. 16 Since these cases shared similar clinical manifestations and imaging characteristics, the authors proposed a name of infant OM for these cases.…”

Section: Discussionmentioning

confidence: 99%

An unusual odontogenic myxoma in mandible and submandibular region: a rare case report

G²,

Gao³

et al. 2014

Dentomaxillofacial Radiology

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An otherwise healthy 14-year-old male was referred to our hospital for the evaluation of a mass that was noticed 2 months previously. The mass was located in the left submandibular area. Comprehensive imaging examinations including panoramic radiography, CT and positron emission tomography-CT were performed. Appropriate surgical management and histopathological examination were taken for the patient. Histopathological examination demonstrated an odontogenic myxoma.

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Pediatric odontogenic fibromyxoma of the mandible: Case report and review of the literature

Haser

Hernández-Prera³

et al. 2015

Head & Neck

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Infant Odontogenic Myxoma: A specific entity

Cited by 19 publications

References 17 publications

Infant Odontogenic Myxoma: Case Report and Literature Review of a Specific Entity Recently Described

Infant Odontogenic Myxoma: Case Report and Literature Review of a Specific Entity Recently Described

An unusual odontogenic myxoma in mandible and submandibular region: a rare case report

Pediatric odontogenic fibromyxoma of the mandible: Case report and review of the literature

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