Multiple bilateral supernumerary mandibular premolars in a non-syndromic patient with associated orthokeratised odontogenic cyst- A case report and review of literature

Abstract

Multiple supernumerary teeth are very rare, accounting for less than 1% of cases. They are commonly associated with syndromes like Gardner's syndrome and cleidocranial dysostosis and cleft lip and palate. Non-syndromic multiple supernumerary teeth have a predilection to occur in the mandibular premolar region. Orthokeratinized odontogenic cyst (OOC) is a relatively uncommon developmental cyst comprising about 10% of the cases that had been previously implied as odontogenic keratocysts. More than half of the cases of OOC are associated with impacted tooth; but not a single case of OOC associated with supernumerary teeth is reported. Hence, the purpose of this article is to report the first case of multiple supernumerary mandibular premolars associated with OOC in a 35-year-old male and to review the literature associated with multiple bilateral supernumerary mandibular premolars.

Bilateral orthokeratinized odontogenic cyst: A rare case report and review

“…Literature review[ 3 9 10 11 12 13 14 15 ] showed that the bilateral occurrence of jaw cysts is an uncommon phenomenon [ Table 1 ]. Among the jaw cysts, OKC most commonly showed bilateral occurrence followed by dentigerous cyst.…”

Multiple Orthokeratinized Odontogenic Cysts: A Case Report

“…It occurs in the jaw bones and about 1/2 to 2/3 of the cases have been reported to be associated with an impacted tooth [3,8], or have presented clinically as dentigerous cysts [5]. Sporadic OOC has been recently reported to be associated with two supernumerary teeth [9]. To the best of our knowledge, the presenting case is the first case of multiple OOCs occurring in the same individual, and each of the four OOCs was associated with the impacted 3rd molar in each quadrant.…”

Orthokeratinized odontogenic cyst of the maxilla: report of a case and review of the literature

“…Kasat et al reported a case of OOC with multiple supernumerary teeth (9). rare cases of bilateral involvement of the mandible, dysplastic changes in the epithelial lining of the OOC, association of the OOC with the calcifying odontogenic cyst and complex odontoma have additionally been reported in the literature (10)(11)(12).…”