In a 36-year-old woman with monosymptomatic haematuria, urography showed moderate left-sided hydronephrosis and hydroureter. Five years later the dilation had increased and laparotomy showed a short stricture distally in the left ureter. Microscopy revealed external and internal ureteral endometriosis. Resection of the stricture was followed by regression of the dilation. To avoid irreversible kidney damage from unrecognized ureteral endometriosis, all known endometriosis patients should undergo urography.