Spontaneous Regression of a Plaque‐Type Striated Muscle Hamartoma

Abstract

Striated muscle hamartoma (SMH) is a rare, congenital or acquired, benign tumor that predominantly affects children. Therapeutic management has classically been surgical intervention. We present a pediatric case of a facial plaque-type SMH with spontaneous regression that highlights the importance of clinical observation for a conservative approach.

Plaque‐Type Variant of Acquired Rhabdomyomatous Mesenchymal Hamartoma on the Chin: A Case Series

“…Seven patients had plaque-type or subcutaneous lesions. 3–6,10,12,13 Three cases demonstrated a skin-colored plaque on the chin in adulthood, 3–5 2 showed red plaques in newborns, 10,13 one had a facial lesion resembling en coup de sabre, 6 and another had a deep subcutaneous nodule in the sternoclavicular area. 12 Only 4 lesions were located on the chin 3–5,13 and one of them was a congenital RMH.…”

“…[3][4][5][6]10,12,13 Three cases demonstrated a skin-colored plaque on the chin in adulthood, 3-5 2 showed red plaques in newborns, 10,13 one had a facial lesion resembling en coup de sabre, 6 and another had a deep subcutaneous nodule in the sternoclavicular area. 12 Only 4 lesions were located on the chin [3][4][5]13 and one of them was a congenital RMH. 13 Three cases of similar acquired plaque-type RMH have been reported previously, including case 1 in this series.…”

“…12 Only 4 lesions were located on the chin [3][4][5]13 and one of them was a congenital RMH. 13 Three cases of similar acquired plaque-type RMH have been reported previously, including case 1 in this series. 3 The second case reported by Chang et al was a 40-year-old Asian woman who had a fresh-colored plaque on her right upper chin for 10 years.…”

Smooth muscle hamartoma and striated muscle hamartoma: Clinicopathologic characterization of two rare entities and literature review

“…Histopathologically the lesions were characterized by striated muscle proliferation on the dermis. Since then more than 60 cases have been reported in the literature, with a preference for pediatric patients, especially for newborns and infants, arguing for a true congenital nature to this lesion 13,36‐58 . To date, the largest case series described five cases, with three cases presenting in the pediatric age and the remaining two cases presenting in a 48‐ and a 54‐year‐old patients 14 .…”

“…Clinically, SMHs muscle hamartomas have a broad presentation ranging from a skin tag, 13,14,37,38,43,49,50,58 a mass-forming lesion, 36,40,41,44,45,51,53,[55][56][57]60,61 a papule/plaque/nodule, 14,39,[46][47][48]54,59,[62][63][64] a polypoid mass, 52 and a cystic lesion. 42 Of our six cases with clinical description, available two cases presented as papule/plaque, two as a mass, one as a skin tag, and one as a pigmented lesion.…”