Ophthalmomyiasis is the infestation of human eye with larvae of certain flies. Only a few cases of Ophthalmomyiasis externa have been reported from India. We report a human case of external ophthalmomyiasis caused by the larva of oestrus ovis (sheep botfly) for the first time, to the best of our knowledge, from Sonbhadra district of Uttar Pradesh. A 32 year old male patient presented with redness and watering in the right eye. A moving larva was found in his right inferior fornix and after its removal, the symptoms improved after a few hours.