Odontogenic Keratocysts (OKCs) are rare cystic lesions known for their aggressive behavior and tendency to recur after excision. These benign tumors usually occur in the mandible or maxilla and are believed to arise from the dental lamina. The medical community is still debating whether these lesions are developmental or neoplastic [1]. However, most experts agree that they are locally aggressive and require prompt treatment to avoid complications. On imaging, they typically appear as a solitary unilocular lesion that extends longitudinally in the posterior portions of the mandible. Although most are solitary, multiple odontogenic keratocysts can also be present in some cases, and an associated condition such as basal cell nevus syndrome should be considered. It’s worth noting that involvement of the maxillary sinus by OKC is rare, but it can happen [2]. The maxillary sinus is part of the paranasal sinuses, which are in proximity to developing tooth and root apices of premolar and molars. The overlapping of various structures makes it challenging to diagnose such lesions via maxillary radiographs. Therefore, prompt diagnosis and treatment of OKCs is essential to prevent further complications [3].